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Isolated cases of PNET have been reported in visceral sites, such as the kidneys, uterus, ovaries, testicles, bladder, and pancreas. The occurrence of these tumors in the head and neck region is very rare. Purpose: We report the case of a 37-year-old patient with a PNET of the amygdala and a favorable outcome after induction chemotherapy followed by exclusive radiotherapy. Results: The patient exhibited a significant clinical and radiological response to the first-line chemotherapy regimen (VAC-IE) followed by radiotherapy. The treatment led to a complete clinical and radiological response. Currently, the patient is alive and in good health, with no signs of local recurrence or metastasis three years post-treatment. Conclusion: PNETs of the amygdala are extremely rare and aggressive. A combined therapeutic approach involving surgery, chemotherapy, and radiotherapy is essential for effective treatment. This case demonstrates that aggressive treatment can lead to favorable outcomes even in rare tumor locations. Niama Ghozali, Hajar Bakouri, Kamal Saiss, Yassine Sbaiti, Khadija Darif, Mounia Amzerin, Nabila Sella, Mohammed El Hfid, Fatima Zahra El M’Rabet Adobe PDF Library 11.0 Primitive Neuroectodermal Tumor (PNET), Amygdala, Chemotherapy, Radiotherapy, Surgery D:20240628063828 Background: The primitive neuroectodermal tumor (PNET) belongs to the family of malignant small round cell tumors with neuroepithelial differentiation. Isolated cases of PNET have been reported in visceral sites, such as the kidneys, uterus, ovaries, testicles, bladder, and pancreas. The occurrence of these tumors in the head and neck region is very rare. Purpose: We report the case of a 37-year-old patient with a PNET of the amygdala and a favorable outcome after induction chemotherapy followed by exclusive radiotherapy. Results: The patient exhibited a significant clinical and radiological response to the first-line chemotherapy regimen (VAC-IE) followed by radiotherapy. The treatment led to a complete clinical and radiological response. Currently, the patient is alive and in good health, with no signs of local recurrence or metastasis three years post-treatment. Conclusion: PNETs of the amygdala are extremely rare and aggressive. A combined therapeutic approach involving surgery, chemotherapy, and radiotherapy is essential for effective treatment. This case demonstrates that aggressive treatment can lead to favorable outcomes even in rare tumor locations. endstream endobj 22 0 obj <>stream h24T0Pw/+Q0L)646)I0ibC* RS  endstream endobj 23 0 obj <>stream hތTn6 [m̱(R $X_NYbBI9ubOGMu$dzhކںލ~et=?#5ݱ~@B\TLKvj3k4oSf@7+t'Zs\i MWU蒃ѿs8~s 6[6Ț%-g|:i|j<~u?YfyY([e2c&X }FʌUQO֕rЍJl).*p6Ѻ_ J46x-v׺Jܾ?Q>SX9[޼jyITl8G!6JʣF79 {x(gt_ m9p /8Q.ښSF= VUM GM9kI~G t#NLP!}VCle/>v'Sr.(C;!xmQQFq-O|P/TĀ@&QlQ 07.8;Q i*P i? 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